Torticollis is commonly termed as "wry neck". In torticollis, there is abnormal posturing of the head and neck due to the shortening of sternocleidomastoid muscle. Torticollis causes tipping of the head towards the shortened sternocleidomastoid which results in rotation of chin to the opposite side. It is a common disorder which can occur at all ages, from newborns to adults. It can develop prenatally (congenital) or postnatally (acquired). This case report highlights the various craniofacial features in a 5-year-old male patient presented with torticollis. During examination, patient had asymmetry of face, short and tight sternocleidomastoid which was band shape in affected site, spastic contralateral sternocleidomastoid and decreased range of motion of neck. Intraorally, patient had multiple carious tooth and macroglossic tongue. The craniofacial features play a significant role in the identification of torticollis and hence, can be helpful in early detection. It requires a multidisciplinary approach for its treatment. How to cite this article: Eranhikkal A, Goswami M. Neglected Torticollis: A Rare Pediatric Case Report. Int J Clin Pediatr Dent 2020;13(1):94-97.