Cutaneous leishmaniasis (CL) is a self-curing skin infection distributed in tropics and sub-tropics. Up to one million cases of CL appeared in endemic areas a year. Leishmanization (artificially controlled infections) was widely used to control cutaneous leishmaniasis in the past. Basal cell carcinoma (BCC) is the most common epithelial neoplasm of the skin. Cases of BCC developing in a leishmanial scar have been documented. We present the first case of confirmed basal cell carcinoma arising in 2020 in an 81-old physician working in Moscow (Russian Federation) in a leishmanial scar. It was 50 years after the primary lesion due to a successful leishmanization, widely used to control cutaneous leishmaniasis in the past.